Phosphorus MR spectroscopy shows a tissue specific in vivo distribution of biochemical expression of the G3460A mutation in Leber's hereditary optic neuropathy.

نویسندگان

  • R Lodi
  • V Carelli
  • P Cortelli
  • S Iotti
  • M L Valentino
  • P Barboni
  • F Pallotti
  • P Montagna
  • B Barbiroli
چکیده

Occipital lobe and calf muscle energy metabolism were studied in vivo by magnetic resonance spectroscopy (31P-MRS) in four members of a family harbouring the mitochondrial DNA G3460A mutation causing Leber's hereditary optic neuropathy (LHON). Three siblings carried 100% mutated mitochondrial DNA (homoplasmy), while their mother had coexistence of mutated and wild-type mitochondrial DNA (heteroplasmy). Indices of brain energy metabolism on 31P-MRS were abnormal in all subjects examined, but the muscle oxidative phosphorylation rate was normal. These findings indicate a tissue specific distribution of the biochemical expression of the G3460A LHON mutation and suggest that extramitochondrial factors, such as nuclear genes, may influence expression of this mutation in vivo.

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عنوان ژورنال:
  • Journal of neurology, neurosurgery, and psychiatry

دوره 72 6  شماره 

صفحات  -

تاریخ انتشار 2002